Intramuscular lipoma is an unusual benign mesenchymal tumor, which infiltrates the skeletal muscle, and in exceedingly rare cases can occur on the head or neck. Intramuscular lipoma is composed of mature adipose tissue that infiltrates muscle in a diffuse manner, and the entrapped muscle fibers exhibit varying degrees of atrophic change. Because of infiltrating features of adipocyte, the recurrence rate after excision is very high. We herein report two cases of intramuscular lipoma of the chin.